A Two-Year-Old Boy with Diphallia and Multiple Congenital Anomalies

Authors

  • Rizal Trianto Department of Urology, Faculty of Medicine, Universitas Brawijaya
  • Pradana Nurhadi Department of Urology, Faculty of Medicine, Universitas Brawijaya
  • Besut Daryanto https://orcid.org/0000-0002-0776-1633, Saiful Anwar Hospital http://orcid.org/0000-0002-0776-1633

DOI:

https://doi.org/10.21776/ub.jkb.2022.032.02.10

Keywords:

Diphallia, multiple anomalies

Abstract

Diphallia is a rare urogenital defect and varies from a small accessory penis or duplication of the glans to complete penile duplication. Its incidence is 1 in 5.5 million live births. Only 100 cases were reported from 1609 until 2021. A two-year-old boy with diphallia and multiple congenital anomalies had an uncircumcised penis with two glans penis and two complete urethral orifices, accompanied by scrotum bifidum, asymmetric right buttock, with normal anorectal position. Spina bifida with lipomyelocele, tethered cord at the level of vertebra lumbar 3-4, scrotum bifidum, and left mild hydronephrosis were observed using Magnetic Resonance Imaging (MRI). Urethrocystoscopy of both complete urethra revealed meatal stenosis and bulbar urethral stricture, normal posterior urethral, and no verumontanum in the right urethral orifice and did dilatation. Whereas normal urethral orifice, anterior urethra, posterior urethra and verumontanum were found in the left side. Management for diphallia must consider associated anomalies and the goal of patient satisfaction. In this case, conservative treatment is the best choice.

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Author Biography

Besut Daryanto, https://orcid.org/0000-0002-0776-1633, Saiful Anwar Hospital

Department of Urology, Brawijaya University

References

Frolov A, Tan Y, Rana MW, and Martin III JR. A Rare Case of Human Diphallia Associated with Hypospadias. Case Reports in Urology. 2018; 2018: 1-6

Bhat HS, Sukumar S, Nair TB, and C. Saheed SM. Successful Surgical Correction of True Diphallia, Scrotal Duplication, and Associated Hypospadias. Journal of Pediatric Surgery. 2006; 41(10): 13-14.

Maharani TK. (Online) 2013. Faktor-Faktor yang Berpengaruh terhadap Kejadian Kelainan Kongenital Sistem Urogenital pada Neonatus. https://media.neliti.com/media/publications/112788-ID-faktor-faktor-yang-berpengaruh-terhadap.pdf [accessed 2019 May 23]

Mirshemirani AR, Sadeghyian N, Mohajerzadeh L, Molayee H, and Ghaffari P. Diphallus: Report on Six Cases and Review of the Literature. Iranian Journal of Pediatrics. 2010; 20(3): 353-357.

Gyftopoulos K, Wolffenbuttel KP, and Nijman RJM. Clinical and Embryologic Aspects of Penile Duplication and Associated Anomalies. Urology. 2002: 60(4): 675–679.

Torres ME, Sanchez PJC, Aragon TA, Camacho TV, and Colorado GA. Diphallia. Revista Mexicana de Urolog´ıa. 2009; 69(1): 32–35.

Mandal A dan Sahi PK. Complete Diphallus. BAOJ Pediatrics. 2017; 3(2): 1-3

Acimi S. Complete Diphallia. Scandinavian Journal of Urology and Nephrology. 2008; 38(5): 389-391.

Kouka SCN, Diallo Y, Millogo S, et al. Penile Duplication: A Case Report. Medical & Surgical Urology. 2016; 5(1): 1-2

Levin T, Han B, and Little BP. Congenital Anomalies of the Male Urethra. Pediatrics Radiology. 2007; 37(9): 851-862.

Sharma N, Gupta S, Goyal M, and Sattavan S. Complete Diphallia with No Other Associated Congenital Anomaly. International Journal of Medical Pediatrics and Oncology. 2017; 3(3): 136-136

Warf BC, Scott MR, Barnes PD, and Hendren III WH. Tethered Spinal Cord in Patients with Anorectal and Urogenital Malformations. Pediatric Neurosurgeon. 1993; 19(1): 25-30.

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Published

2022-08-31 — Updated on 2022-11-04

Versions

Issue

Vol. 32 No. 2 (2022)

Section

Case Report

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